Annotated protein: | Acetylcholine receptor subunit delta. Gene symbol: CHRND. Taxonomy: Homo sapiens (Human). Uniprot ID: Q07001 |
antibody wiki: | |
SynGO gene info: | SynGO data @ CHRND |
Ontology domain: | Biological Process |
SynGO term: | transmitter-gated ion channel activity involved in regulation of postsynaptic membrane potential (GO:1904315) |
Synapse type(s): | Neuro-muscular junction |
Annotated paper: | Brownlow S, et al. "Acetylcholine receptor delta subunit mutations underlie a fast-channel myasthenic syndrome and arthrogryposis multiplex congenita" J Clin Invest. 2001 Jul;108(1):125-30 PMID:11435464 |
Figure(s): | Fig.2-4 |
Annotation description: | Fig.1: congenital myasthenic syndrome patient has a E59K mutation in the nAChR delta subunit. Fig.2+3+4: The mutation was shown to affect channel kinetics with heterologous expression of WT and δE59K mutant receptors in HEK cells. Note: data to support the action of this mutation in situ is not included in this paper, but the annotation to the term 'transmitter-gated ion channel activity involved in regulation of postsynaptic membrane potential (GO:1904315)' is based on the presence the myasthenic syndrome in the mutation carrier and the well established localization of the nAChR in the postsynaptic membrane of muscle fibers. |
Evidence tracking, Biological System: | Intact tissue Non-neuronal tissue |
Evidence tracking, Protein Targeting: | Genetic transformation (eg; knockout, knockin, mutations) Over-expression |
Evidence tracking, Experiment Assay: | Whole-cell patch clamp |
Annotator(s): | Pim van Nierop (ORCID:0000-0003-0593-3443) Guus Smit (ORCID:0000-0002-2286-1587) Matthijs Verhage (ORCID:0000-0002-2514-0216) |
Lab: | Department of Functional Genomics, Department of Molecular and Cellular Neurobiology, Center for Neurogenomics and Cognitive Research, Vrije Universiteit Amsterdam, 1081 HV Amsterdam, The Netherlands |
SynGO annotation ID: | 1982 |
Dataset release (version): | 20231201 |
View annotation as GO-CAM model: |